CClinicalTrials.gg
TerminatedNCT01811875Updated Jul 22, 2021Results posted

Post-Marketing Safety Study Following Long-Term Prophylactic OptivateTreatment in Subjects With Severe Haemophilia A

A Phase 4 interventional study of Optivate 500IU in Haemophilia A, sponsored by Bio Products Laboratory. Terminated at 4 sites in 3 countries. Per ClinicalTrials.gov, last updated 2021-07-22.

Sponsored by Bio Products Laboratory · Phase 4, Interventional, and Treatment

Why this study was terminated
Study no longer required as Optivate German license expired in Sep-2017.
Phase
Phase 4
Study type
Interventional
Enrollment
7
Allocation
Not applicable
Sex
All
01

Study summary

Primary objective: To assess post-marketing immunogenicity of Optivate® by monitoring plasma inhibitor levels for at least 100 Exposure Days (EDs) for each subject.

Secondary objectives: To assess efficacy and tolerability by monitoring FVIII recovery and adverse events

Read the detailed description

The primary efficacy endpoint is to assess immunogenicity of Optivate® by monitoring plasma inhibitor level for at least 100 EDs for each subject.

FVIII inhibitor evaluation FVIII inhibitor screen data will be listed. FVIII quantitative inhibitor results will be listed. Shift tables will present the number of subjects with positive (≥ 0.6 BU) and negative (\< 0.6 BU) results and those for whom the results change during the study. The number of exposure days until development of inhibitors will be summarised.

For the secondary endpoints: Descriptive statistics will be presented on the number of recoveries at each timepoint and for each subject. These will be presented for each visit and for each subject and then for each batch of FVIII/ Optivate® used. All the AE data (from CRF and study diary) will be pooled together and reported in terms of the type, duration, treatment and/or severity.

02

Conditions studied

  • Haemophilia A

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Keywords

  • Haemophilia A
03

Who can participate

Ages eligible
Child (0–17), Adult (18–64), Older adult (65+)
Sexes eligible
All
Accepts healthy volunteers
No

Inclusion criteria

  • Written informed consent or, if less than 18 years of age written assent (where possible) and their parent/guardian's written informed consent.
  • Severe haemophilia A (\< 1%# FVIII:C).
  • Previously Treated Patients (PTPs) with > 150 exposure days on prior Factor VIII therapy (of which at least the last 50 EDs or 2 years treatment can be confirmed by way of subject records).
  • Immunocompetent with CD4 count > 200 / µl.
  • HIV negative or a viral load \< 200 particles / µl.

    • subjects suffering from severe haemophilia A (\<2%) may be enrolled, but only after approval by BPL. Subjects with a Factor VIII of \<2% may not constitute more than 50% of the total patient population. A separate statistical evaluation will be conducted for the \<1% and \<2% populations.

Exclusion criteria

Exclusion Criteria:

    • History of inhibitor development to FVIII or a positive result on the Nijmegen Bethesda at screening (quantitative result of > 0.6 BU) prior to the administration of Optivate®.

      • Known or suspected hypersensitivity to the investigational medicinal product or its excipients.
      • Clinically significant liver disease, renal disease, or coagulopathy other than haemophilia A.
      • History of unreliability or non cooperation (including not being able to complete the study diary).
      • Participating in, or have taken part in another trial within the last 30 days.
04

Study design

Phase
Phase 4
Primary purpose
Treatment
Allocation
Not applicable
Intervention model
Single group
Masking
None (open label)
Enrollment
7 participants (actual)

Study arms

  • Experimental
    Optivate 500IU

    Optivate 500IU

    Biological: Optivate 500IU

Interventions

  • BiologicalOptivate 500IU
05

What researchers measure

Primary outcomes

  1. Number of Participants That Did Not Develop Inhibitors to FVIII (<0.6BU)

    FVIII inhibitor status at any of the study visits was measured by a Nijmegen Bethesda assay and inhibitor screens. A result of ≥ 0.6 BU confirmed that the subject had developed inhibitors to FVIII. If this occurred, the test was repeated on a separate sample; if both tests were confirmed to be ≥ 0.6 BU, this was to be reported by the Investigator as a serious adverse event (SAE).

    Time frame: At least 100 Exposure Days for each subject. Subjects will attend 5 visits over a period of up to 12 months

Secondary outcomes

  1. Recovery With Prior FVIII Concentrate (Screening Visit) Versus Recovery With First Dose With Optivate® (Visit 1) for the Protocol Population.

    Recovery with prior FVIII concentrate (Screening Visit) versus recovery with first dose with Optivate® (Visit 1) for the protocol population.

    Time frame: Screening and Visit 1 (up to 4 weeks)

  2. Optivate® Recovery Across Visits 1 to 4 for the Protocol Population.

    A recovery assessment was conducted at each study visit. Recovery assessments were only conducted after a 3-day washout period and when the subject was not actively bleeding. At the Screening Visit, subjects who had completed a 3-day washout period and were not actively bleeding were dosed with 30 IU/kg of their prior FVIII concentrate. The dose was measured to the nearest 0.1 mL. Blood samples for the recovery assessment were to be collected at the following time points: * Predose * 15 minutes postinfusion (±5 minutes). * 30 minutes postinfusion (±5 minutes). * 1 hour postinfusion (±10 minutes). Actual times of sample collection were to be recorded in the CRF At visits 1, 2, 3 and 4 subjects were dosed with 30 IU/kg of Optivate and blood samples for recovery assessments were taken at the same timepoints as specified above. An ANOVA model (analysis of variance) was used to calculate the adjusted mean for recovery across visits 1 to 4.

    Time frame: Visits 1 to 4 (Up to 100 Optivate exposure days)

  3. Optivate® Therapy to Treat Breakthrough Bleeds Per Subject Per Year in the Protocol Population.

    Optivate® therapy to treat number of breakthrough bleeds per subject per year in the protocol population over a period of 12 months.

    Time frame: Over a period of 12 months

  4. Overall Consumption of Optivate®: Number of Exposure Days for Each Subject Per Year/Subject in the Per Protocol Population.

    Overall consumption of Optivate®: Number of exposure days for each subject per year/subject in the per protocol population over a period of 12 months.

    Time frame: Over a period of 12 months

  5. Overall Consumption of Optivate®: Total Dose in IU/kg of Optivate® Per Subject for Prophylactic Use.

    Overall consumption of Optivate®: Total dose in IU/kg of Optivate® per subject for prophylactic use over a period of 12 months.

    Time frame: Over a period of 12 months

  6. Overall Consumption of Optivate®: Total Dose in IU/kg of Optivate® Per Subject to Treat a Bleed in the Protocol Population.

    Overall consumption of Optivate®: Total dose in IU/kg of Optivate® per subject to treat a bleed in the protocol population over a period of 12 months.

    Time frame: Over a period of 12 months

  7. Overall Consumption of Optivate®: Total Number of Infusions for Prophylactic Use Per Subject in the Protocol Population.

    Overall consumption of Optivate®: Total number of infusions for prophylactic use per subject in the protocol population.

    Time frame: Over a period of 12 months

  8. Overall Consumption of Optivate®: Total Number of Infusions to Treat a Bleed Per Subject in the Protocol Population.

    Total number of infusions to treat a bleed per subject in the protocol population.

    Time frame: Over a period of 12 months

  9. Overall Consumption of Optivate®: Overall Mean Dose in IU/kg of Optivate® Per Subject/Year for Prophylactic Use in the Protocol Population.

    Overall consumption of Optivate®: Overall mean dose in IU/kg of Optivate® per subject/year for prophylactic use in the protocol population.

    Time frame: Over a period of 12 months

  10. Treatment Emergent Adverse Events (Non-serious) in the Safety Population

    Treatment emergent adverse events (non-serious) in the safety population.

    Time frame: Over a period of 12 months

  11. Treatment Emergent Adverse Events (Serious) in Safety Population

    Treatment emergent adverse events (serious) in safety population over a period of 12 months

    Time frame: Over a period of 12 months

  12. Number of Participants With Inhibitor Development in Safety Population (Measured by ≥0.6 Bethesda Units)

    Inhibitor Development: Positive FVIII inhibitor status in safety population measured by ≥0.6 Bethesda units (this was a safety measurement but was assessed as a primary efficacy endpoint).

    Time frame: Over a period of 12 months

06

Results

Posted Jul 22, 2021

Participant flow

Seven patients were enrolled. One patient in Germany; 4 patients in Colombia and 2 patients in Poland.

Participant flow — Overall Study
MilestoneOptivate 500IU
Started7
Completed5
Not completed2

Outcome measures

PrimaryNumber of Participants That Did Not Develop Inhibitors to FVIII (<0.6BU)

FVIII inhibitor status at any of the study visits was measured by a Nijmegen Bethesda assay and inhibitor screens. A result of ≥ 0.6 BU confirmed that the subject had developed inhibitors to FVIII. If this occurred, the test was repeated on a separate sample; if both tests were confirmed to be ≥ 0.6 BU, this was to be reported by the Investigator as a serious adverse event (SAE).

Time frame:
At least 100 Exposure Days for each subject. Subjects will attend 5 visits over a period of up to 12 months
Reported as:
Count of participants · Participants
Number of Participants That Did Not Develop Inhibitors to FVIII (<0.6BU)
ParticipantsOptivate 500IU
Number of Participants That Did Not Develop Inhibitors to FVIII (<0.6BU)5
SecondaryRecovery With Prior FVIII Concentrate (Screening Visit) Versus Recovery With First Dose With Optivate® (Visit 1) for the Protocol Population.

Recovery with prior FVIII concentrate (Screening Visit) versus recovery with first dose with Optivate® (Visit 1) for the protocol population.

Time frame:
Screening and Visit 1 (up to 4 weeks)
Reported as:
Mean · IU/dL per IU/kg
Recovery With Prior FVIII Concentrate (Screening Visit) Versus Recovery With First Dose With Optivate® (Visit 1) for the Protocol Population.
IU/dL per IU/kgOptivate 500IU
Recovery With Prior FVIII Concentrate (Screening Visit) Versus Recovery With First Dose With Optivate® (Visit 1) for the Protocol Population.-0.91 (-1.87 to 0.04)
SecondaryOptivate® Recovery Across Visits 1 to 4 for the Protocol Population.

A recovery assessment was conducted at each study visit. Recovery assessments were only conducted after a 3-day washout period and when the subject was not actively bleeding. At the Screening Visit, subjects who had completed a 3-day washout period and were not actively bleeding were dosed with 30 IU/kg of their prior FVIII concentrate. The dose was measured to the nearest 0.1 mL. Blood samples for the recovery assessment were to be collected at the following time points: * Predose * 15 minutes postinfusion (±5 minutes). * 30 minutes postinfusion (±5 minutes). * 1 hour postinfusion (±10 minutes). Actual times of sample collection were to be recorded in the CRF At visits 1, 2, 3 and 4 subjects were dosed with 30 IU/kg of Optivate and blood samples for recovery assessments were taken at the same timepoints as specified above. An ANOVA model (analysis of variance) was used to calculate the adjusted mean for recovery across visits 1 to 4.

Time frame:
Visits 1 to 4 (Up to 100 Optivate exposure days)
Reported as:
Mean · IU/dL per IU/kg
Optivate® Recovery Across Visits 1 to 4 for the Protocol Population.
IU/dL per IU/kgOptivate 500IU
Optivate® Recovery Across Visits 1 to 4 for the Protocol Population.-0.01 (-1.72 to 1.70)
SecondaryOptivate® Therapy to Treat Breakthrough Bleeds Per Subject Per Year in the Protocol Population.

Optivate® therapy to treat number of breakthrough bleeds per subject per year in the protocol population over a period of 12 months.

Time frame:
Over a period of 12 months
Reported as:
Mean · Bleeds per subject per year
Optivate® Therapy to Treat Breakthrough Bleeds Per Subject Per Year in the Protocol Population.
Bleeds per subject per yearOptivate 500IU
Optivate® Therapy to Treat Breakthrough Bleeds Per Subject Per Year in the Protocol Population.3.99 ± 2.961
SecondaryOverall Consumption of Optivate®: Number of Exposure Days for Each Subject Per Year/Subject in the Per Protocol Population.

Overall consumption of Optivate®: Number of exposure days for each subject per year/subject in the per protocol population over a period of 12 months.

Time frame:
Over a period of 12 months
Reported as:
Mean · Days
Overall Consumption of Optivate®: Number of Exposure Days for Each Subject Per Year/Subject in the Per Protocol Population.
DaysOptivate 500IU
Overall Consumption of Optivate®: Number of Exposure Days for Each Subject Per Year/Subject in the Per Protocol Population.116.2 ± 18.12
SecondaryOverall Consumption of Optivate®: Total Dose in IU/kg of Optivate® Per Subject for Prophylactic Use.

Overall consumption of Optivate®: Total dose in IU/kg of Optivate® per subject for prophylactic use over a period of 12 months.

Time frame:
Over a period of 12 months
Reported as:
Mean · IU/kg
Overall Consumption of Optivate®: Total Dose in IU/kg of Optivate® Per Subject for Prophylactic Use.
IU/kgOptivate 500IU
Overall Consumption of Optivate®: Total Dose in IU/kg of Optivate® Per Subject for Prophylactic Use.3639.97 ± 993.464
SecondaryOverall Consumption of Optivate®: Total Dose in IU/kg of Optivate® Per Subject to Treat a Bleed in the Protocol Population.

Overall consumption of Optivate®: Total dose in IU/kg of Optivate® per subject to treat a bleed in the protocol population over a period of 12 months.

Time frame:
Over a period of 12 months
Reported as:
Mean · IU/kg
Overall Consumption of Optivate®: Total Dose in IU/kg of Optivate® Per Subject to Treat a Bleed in the Protocol Population.
IU/kgOptivate 500IU
Overall Consumption of Optivate®: Total Dose in IU/kg of Optivate® Per Subject to Treat a Bleed in the Protocol Population.97.72 ± 117.086
SecondaryOverall Consumption of Optivate®: Total Number of Infusions for Prophylactic Use Per Subject in the Protocol Population.

Overall consumption of Optivate®: Total number of infusions for prophylactic use per subject in the protocol population.

Time frame:
Over a period of 12 months
Reported as:
Mean · Infusions
Overall Consumption of Optivate®: Total Number of Infusions for Prophylactic Use Per Subject in the Protocol Population.
InfusionsOptivate 500IU
Overall Consumption of Optivate®: Total Number of Infusions for Prophylactic Use Per Subject in the Protocol Population.116.8 ± 17.66
SecondaryOverall Consumption of Optivate®: Total Number of Infusions to Treat a Bleed Per Subject in the Protocol Population.

Total number of infusions to treat a bleed per subject in the protocol population.

Time frame:
Over a period of 12 months
Reported as:
Mean · Infusions
Overall Consumption of Optivate®: Total Number of Infusions to Treat a Bleed Per Subject in the Protocol Population.
InfusionsOptivate 500IU
Overall Consumption of Optivate®: Total Number of Infusions to Treat a Bleed Per Subject in the Protocol Population.2.4 ± 3.21
SecondaryOverall Consumption of Optivate®: Overall Mean Dose in IU/kg of Optivate® Per Subject/Year for Prophylactic Use in the Protocol Population.

Overall consumption of Optivate®: Overall mean dose in IU/kg of Optivate® per subject/year for prophylactic use in the protocol population.

Time frame:
Over a period of 12 months
Reported as:
Mean · IU/kg
Overall Consumption of Optivate®: Overall Mean Dose in IU/kg of Optivate® Per Subject/Year for Prophylactic Use in the Protocol Population.
IU/kgOptivate 500IU
Overall Consumption of Optivate®: Overall Mean Dose in IU/kg of Optivate® Per Subject/Year for Prophylactic Use in the Protocol Population.3890.02 ± 1033.993
SecondaryTreatment Emergent Adverse Events (Non-serious) in the Safety Population

Treatment emergent adverse events (non-serious) in the safety population.

Time frame:
Over a period of 12 months
Reported as:
Number · treatment emergent events
Treatment Emergent Adverse Events (Non-serious) in the Safety Population
treatment emergent eventsOptivate 500IU
Treatment Emergent Adverse Events (Non-serious) in the Safety Population5
SecondaryTreatment Emergent Adverse Events (Serious) in Safety Population

Treatment emergent adverse events (serious) in safety population over a period of 12 months

Time frame:
Over a period of 12 months
Reported as:
Number · treatment emergent events
Treatment Emergent Adverse Events (Serious) in Safety Population
treatment emergent eventsOptivate 500IU
Treatment Emergent Adverse Events (Serious) in Safety Population1
SecondaryNumber of Participants With Inhibitor Development in Safety Population (Measured by ≥0.6 Bethesda Units)

Inhibitor Development: Positive FVIII inhibitor status in safety population measured by ≥0.6 Bethesda units (this was a safety measurement but was assessed as a primary efficacy endpoint).

Time frame:
Over a period of 12 months
Reported as:
Count of participants · Participants
Number of Participants With Inhibitor Development in Safety Population (Measured by ≥0.6 Bethesda Units)
ParticipantsOptivate 500IU
Number of Participants With Inhibitor Development in Safety Population (Measured by ≥0.6 Bethesda Units)0

Adverse events

Collected over Over a period of 12 months. Non-serious events are listed at a 0% frequency threshold.

Adverse event summary by group
GroupDeathsSeriousOther
Optivate 500IU1/7 (14.3%)2/7 (28.6%)3/7 (42.9%)
Most frequent serious events
Most frequent serious events
EventOptivate 500IU
Fatal road traffic accidentInjury, poisoning and procedural complications1/7
Asthmatic crisisRespiratory, thoracic and mediastinal disorders1/7
Most frequent other events
Most frequent other events
EventOptivate 500IU
COMMON COLDInfections and infestations1/7
ANKLE TRAUMAInjury, poisoning and procedural complications1/7
BRONCHOSPASMRespiratory, thoracic and mediastinal disorders1/7
SOFT TISSUE TRAUMA LEFT HANDInjury, poisoning and procedural complications1/7
ANEMIABlood and lymphatic system disorders1/7
HEMARTHROSIS OF RIGHT ELBOWMusculoskeletal and connective tissue disorders1/7
GENERAL PAINGeneral disorders1/7
JOINT PAINMusculoskeletal and connective tissue disorders1/7
HEMARTHROSIS OF RIGHT KNEEMusculoskeletal and connective tissue disorders1/7

Baseline characteristics

Age, Categorical
Age, Categorical(Participants)Optivate 500IU
<=18 years2
Between 18 and 65 years5
>=65 years0
Age, Continuous
Age, Continuous(Years)Optivate 500IU
Mean23.6 ± 7.37
Sex: Female, Male
Sex: Female, Male(Participants)Optivate 500IU
Female0
Male7
Ethnicity (NIH/OMB)
Ethnicity (NIH/OMB)(Participants)Optivate 500IU
Hispanic or Latino5
Not Hispanic or Latino2
Unknown or Not Reported0
Region of Enrollment
Region of Enrollment(participants)Optivate 500IU
Colombia4
Poland2
Germany1
07

Study locations

4 sites
  • Fundacion BIOS
    Barranquilla, 80-216, Colombia
  • Hospital general de Medellin
    Medellin, 32-102, Colombia
  • HZRM Haemophilia Centre Rhine Main
    Darmstadt, Mörfelden-Walldorf 64546, Germany
  • Wojewodzki Szpital Specjalistyczny im. M. Kopernika
    Lodz, 93-513, Poland
08

References and documents

Study documents

  • Study protocol · Nov 30, 2015
  • Statistical analysis plan · May 21, 2013

Documents are hosted by the registry — open the source record to download them.

09

Registry details

Key details

Study ID
NCT01811875
Lead sponsor
Bio Products Laboratory
Responsible party
Sponsor
First posted
Mar 15, 2013
Start date
Nov 21, 2014
Primary completion
Aug 31, 2017
Completion
Aug 31, 2017
Results posted
Jul 22, 2021
Last update
Jul 22, 2021

Study contacts

Eric Wolford
study director · Bio Products Laboratory

Oversight

Data monitoring committee
No
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