CClinicalTrials.gg
RecruitingNCT07844590Updated Sep 28, 2026

Developing New Ways to Detect Respiratory Impairment Early in ALS

An observational study in Amyotrophic Lateral Sclerosis (ALS), sponsored by Thomas Jefferson University. Recruiting at 1 site in United States. Open to participants aged 18 Years and older, including healthy volunteers. Per ClinicalTrials.gov, last updated 2026-09-28.

Sponsored by Thomas Jefferson University · Observational

Study type
Observational
Model
Cohort
Time perspective
Prospective
Enrollment
70
Ages
18 Years and older
Sex
All
01

Study summary

The goal of this observational study is to develop new ways to detect early changes associated with amyotrophic lateral sclerosis (ALS), also known as Lou Gehrig's disease. The study will examine whether changes in breathing, magnetic resonance imaging (MRI) of the brainstem and spinal cord, and blood markers can identify early signs of ALS before major physical changes occur.

The main questions the study aims to answer are:

  • Can changes in automatic breathing help identify early ALS-related changes?
  • Can breathing measures distinguish people with ALS from people without ALS?
  • Do people with genetic risk for ALS who show changes in breathing also have changes in the brainstem and spinal cord or higher levels of blood markers associated with nerve damage?

Participants will complete breathing and muscle function tests, an MRI scan of the brainstem and spinal cord, and blood testing. The study will include people with ALS, people with genetic risk for ALS who do not yet have symptoms, and healthy adults for comparison.

02

Conditions studied

  • Amyotrophic Lateral Sclerosis (ALS)

Keywords

  • Amyotrophic lateral sclerosis
  • Early diagnosis
  • Respiratory function
  • Respiratory impairment
  • Respiratory biomarkers
  • Biomarkers
  • Neuroimaging
  • Magnetic resonance imaging
  • Brainstem
  • Spinal cord
  • Neurofilament light chain
  • Genetic risk
  • Presymptomatic amyotrophic lateral sclerosis
  • Motor neuron disease
  • Respiratory muscle function
  • Lou Gehrig's disease
  • automatic breathing
  • respiratory control
  • respiratory weakness
  • respiratory muscle strength
  • pulmonary function
  • respiratory drive
  • hypoxic
  • hypercapnic
  • Surface electromyography
03

Who can participate

Ages eligible
18 Years and older
Sexes eligible
All
Accepts healthy volunteers
Yes
Sampling method
Non-probability sample

Study population

The study population will include adults with symptomatic ALS, asymptomatic or presymptomatic individuals with genetic variants associated with ALS, and healthy age- and sex-matched controls. Participants with ALS or genetic risk for ALS will be recruited from Thomas Jefferson University and other ALS patient inventories and referral sources.

Inclusion criteria

  • Symptomatic participants with ALS must have an ALS Functional Rating Scale-Revised (ALSFRS-R) score of 47/48 or less at the time of recruitment.
  • Asymptomatic/presymptomatic participants must have a pathogenic C9orf72 expansion of at least 25 repeats or a similar genetic abnormality known to be associated with ALS.
  • Healthy control participants must have no clinically identifiable neurological deficits based on medical history and screening. -

Exclusion criteria

Exclusion Criteria:

  • Any safety concern or contraindication to MRI based on MRI safety screening.
  • Healthy control participants who do not pass the neurological screening.
  • Pregnancy.
  • Metal implants above the waist, including cardiac pacemakers or brain, neck, cervical, or thoracic implants.
  • Neurocognitive impairment.
  • Inability or unwillingness to provide informed consent.
  • Younger than 18 years of age.
04

Study design

Observational model
Cohort
Time perspective
Prospective
Enrollment
70 participants (estimated)
Patient registry
No

Groups and cohorts

  • Symptomatic Amyotrophic Lateral Sclerosis

    Participants with symptomatic amyotrophic lateral sclerosis (ALS), including familial or sporadic ALS, who have clinical evidence of disease. This group will undergo study assessments to characterize respiratory function and biomarkers associated with ALS.

  • Asymptomatic/Presymptomatic ALS Gene Carriers

    Participants who carry a genetic variant associated with amyotrophic lateral sclerosis but do not have clinical symptoms or functional deficits associated with ALS. This group will be evaluated for early or subclinical changes in respiratory function and other biomarkers associated with ALS.

  • Healthy Controls

    Neurologically healthy participants without clinically identifiable neurological deficits who will serve as a comparison group for the study assessments.

05

What researchers measure

Primary outcomes

  1. Diagnostic Accuracy of the Automatic Breathing Impairment Risk Score (P0.1 + Chemosensitivity) for Detecting ALS-Related Respiratory Dysfunction

    A linear prediction risk score combining airway occlusion pressure at 0.1 seconds (P0.1) and chemosensitivity will be developed to distinguish symptomatic ALS participants with respiratory dysfunction from healthy controls. Diagnostic performance of the risk score will be evaluated using the area under the receiver operating characteristic curve (ROC-AUC), and an optimal cutoff will be determined. The resulting cutoff will subsequently be used to identify subclinical respiratory impairment in asymptomatic/presymptomatic ALS gene carriers.

    Time frame: During the single study visit

Secondary outcomes

  1. Fractional Anisotropy of the Brainstem and Cervical Spinal Cord

    Fractional anisotropy (FA) will be derived from diffusion tensor imaging of the brainstem and cervical spinal cord to evaluate microstructural abnormalities associated with ALS. FA will be compared among healthy controls and asymptomatic/presymptomatic ALS gene carriers who test positive or negative for automatic breathing impairment.

    Time frame: During the single study visit

  2. Axial Diffusivity of the Brainstem and Cervical Spinal Cord

    Axial diffusivity will be derived from diffusion tensor imaging of the brainstem and cervical spinal cord to evaluate microstructural abnormalities associated with ALS. Measurements will be compared among healthy controls and asymptomatic/presymptomatic ALS gene carriers who test positive or negative for automatic breathing impairment.

    Time frame: During the single study visit

  3. Radial Diffusivity of the Brainstem and Cervical Spinal Cord

    Radial diffusivity will be derived from diffusion tensor imaging of the brainstem and cervical spinal cord to evaluate microstructural abnormalities associated with ALS. Measurements will be compared among healthy controls and asymptomatic/presymptomatic ALS gene carriers who test positive or negative for automatic breathing impairment.

    Time frame: During the single study visit

  4. Mean Diffusivity of the Brainstem and Cervical Spinal Cord

    Mean diffusivity will be derived from diffusion tensor imaging of the brainstem and cervical spinal cord to evaluate microstructural abnormalities associated with ALS. Measurements will be compared among healthy controls and asymptomatic/presymptomatic ALS gene carriers who test positive or negative for automatic breathing impairment.

    Time frame: During the single study visit

  5. Plasma Neurofilament Light Chain (Nf-L) Level

    Neurofilament light chain (Nf-L) levels in plasma will be measured as a blood-based marker of neurodegeneration. Plasma Nf-L levels will be compared among healthy controls and asymptomatic/presymptomatic ALS gene carriers who test positive or negative for automatic breathing impairment to determine whether respiratory impairment is associated with greater evidence of neurodegeneration.

    Time frame: During the single study visit

  6. Serum Neurofilament Light Chain (Nf-L) Level

    Neurofilament light chain (Nf-L) levels in serum will be measured as a blood-based marker of neurodegeneration. Serum Nf-L levels will be evaluated in relation to automatic breathing impairment and compared across study groups as an additional blood-based biomarker of ALS-related neurodegeneration.

    Time frame: During the single study visit.

06

Study locations

1 of 1 sites recruiting
  • Thomas Jefferson University - Center City
    Philadelphia, Pennsylvania 19107, United States
    Recruiting
07

References and documents

Publications

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Individual participant data

Plan to share: Yes — De-identified individual participant data underlying the results reported in study publications will be shared. Data may include demographic and clinical data, functional respiratory measurements, brainstem and spinal cord MRI data, and blood biomarker data, including neurofilament light chain measurements. Data will be shared without direct participant identifiers and in accordance with applicable data use agreements and institutional requirements.

Supporting information: Study protocol

08

Registry details

Key details

Study ID
NCT07844590
Lead sponsor
Thomas Jefferson University
Collaborators
National Institute of Neurological Disorders and Stroke (NINDS)
Responsible party
Jayakrishnan Nair (Principal Investigator, Thomas Jefferson University) — Principal investigator
First posted
Sep 28, 2026
Start date
Sep 2026 (estimated)
Primary completion
Mar 31, 2028 (estimated)
Completion
Mar 31, 2028 (estimated)
Last update
Sep 28, 2026

Study contacts

Jayakrishnan Nair, PhD, PT
Contact
Jayakrishnan.Nair@jefferson.edu
352-871-5888
Dana Johnson, DPT
Contact
dana.johnson@jefferson.edu
215-326-9153

Oversight

Data monitoring committee
No
FDA-regulated drug
No
FDA-regulated device
No
View the source record on ClinicalTrials.gov ↗

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