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TerminatedNCT05683678Updated Apr 4, 2025

US Selumetinib Registry

An observational study in Neurofibromatosis Type 1 and Plexiform Neurofibromas, sponsored by Alexion Pharmaceuticals, Inc.. Terminated at 10 sites in United States. Open to participants aged 2 Years to 18 Years. Per ClinicalTrials.gov, last updated 2025-04-04.

Sponsored by Alexion Pharmaceuticals, Inc. · Observational

Why this study was terminated
Sponsor decision.
Study type
Observational
Model
Case-only
Time perspective
Prospective
Enrollment
37
Ages
2 Years to 18 Years
Sex
All
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Study summary

The purpose of this study is to understand treatment patterns and assess long-term effectiveness and safety outcomes associated with selumetinib treatment as well as to explore clinical and non-clinical factors affecting those outcomes in patients with neurofibromatosis type 1 (NF1) and plexiform neurofibromas (PNs) who started selumetinib between the ages of 2 to 18 years inclusive, and initiated selumetinib treatment on or after 10 April 2020 in a real-world setting.

Read the detailed description

This is a US observational registry of pediatric NF1 PN participants treated with selumetinib.

02

Conditions studied

  • Neurofibromatosis Type 1
  • Plexiform Neurofibromas

Keywords

  • neurofibromatosis type 1
  • plexiform neurofibromas
  • NF1
  • PNs
03

Who can participate

Ages eligible
2 Years to 18 Years
Sexes eligible
All
Accepts healthy volunteers
No
Sampling method
Non-probability sample

Study population

Approximately 200 participants who meet the eligibility criteria will be enrolled from 20-25 sites.

Inclusion criteria

  • Participants diagnosed with NF1 and PN
  • Started selumetinib between the ages of 2 to 18 years inclusive, and initiated selumetinib treatment on or after 10 April 2020, including patients who:
  • Discontinued selumetinib before enrollment; or
  • Initiated treatment before enrollment and are currently on selumetinib; or
  • Initiated selumetinib on the day of enrollment or intend to initiate selumetinib within 3 months after enrollment
  • Able to give written informed consent. Participant or participant's parent/legal guardian must be willing and able to give written informed consent and the participant (if minor) must be willing to give written informed assent.

Exclusion criteria

Exclusion Criteria:

  • Participants currently participating in any clinical trials at time of enrollment or initiation of selumetinib.
04

Study design

Observational model
Case-only
Time perspective
Prospective
Enrollment
37 participants (actual)
Patient registry
No

Groups and cohorts

  • Cohort 1

    Participants who started selumetinib and discontinued selumetinib before enrollment (the "discontinued" cohort).

  • Cohort 2

    Participants who started selumetinib before enrollment and are continuing to receive selumetinib at the time of enrollment (the "continuing" cohort).

  • Cohort 3

    Participants who started selumetinib on the day of enrollment or intend to initiate selumetinib within 3 months after enrollment (the "initiating" cohort).

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What researchers measure

Primary outcomes

  1. Number of Participants with Improvement in Clinically Significant Plexiform Neurofibromas (PNs) as Assessed by the Treating Physician

    Time frame: Up to Month 60

  2. Number of Participants with Improvement in Disease Status as Assessed by the Treating Physician

    Time frame: Up to Month 60

  3. Number of Participants with Improvement in Neurofibromatosis type 1 (NF1) Skeletal Manifestations

    Skeletal manifestations may include changes in the angle of spine curvature.

    Time frame: Up to Month 60

  4. Number of Participants with Treatment Emergent Medical Events of Interest (MEOI)

    Time frame: Up to Month 60

Secondary outcomes

  1. Change From Baseline in the Numerical Rating Scale (NRS-11) Score at Month 60

    Time frame: Baseline, Month 60

  2. Change From Baseline in the Pain Interference Index (PII) Score at Month 60

    Time frame: Baseline, Month 60

  3. Change From Baseline in the Patient Global Impression of Change (GIC) Scale at Month 60

    Time frame: Baseline, Month 60

  4. Change From Baseline in the Pediatric Quality of Life Inventory (PedsQL) at Month 60

    Time frame: Baseline, Month 60

06

Study locations

10 sites
  • Phoenix Children's Hospital
    Phoenix, Arizona 85016, United States
  • Children's Hospital Los Angeles
    Los Angeles, California 90027-6062, United States
  • Nicklaus Children's Hospital
    Miami, Florida 33155, United States
  • Arnold Palmer Hospital For Children
    Orlando, Florida 32806, United States
  • Ochsner Medical Center
    New Orleans, Louisiana 70121, United States
  • Mayo Clinic
    Rochester, Minnesota 55905, United States
  • Albany Medical Center
    Albany, New York 12208, United States
  • The Children's Hospital at Montefiore (CHAM)
    Bronx, New York 10467, United States
  • Waters Center for Childrens Cancer and Blood Disorders
    Syracuse, New York 13210, United States
  • Cook Children's Medical Center
    Fort Worth, Texas 76104, United States
07

References and documents

Individual participant data

Plan to share: Yes — Alexion has a public commitment to allow requests for access to study data and will be supplying a protocol, CSR, and plain language summaries.

Supporting information: Study protocol, Sap, Csr

No publications or documents are linked to this record.

08

Registry details

Key details

Study ID
NCT05683678
Lead sponsor
Alexion Pharmaceuticals, Inc.
Responsible party
Sponsor
First posted
Jan 13, 2023
Start date
Jan 4, 2019
Primary completion
Nov 13, 2024
Completion
Nov 13, 2024
Last update
Apr 4, 2025

Oversight

Data monitoring committee
No
View the source record on ClinicalTrials.gov ↗

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This study is terminated, as verified in Mar 2025. You cannot join it, but the record below documents what was studied.

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