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Active, not recruitingNCT04273243Updated Oct 2, 2025

Long-Term Follow Up of CLN6 Batten Disease Subjects Following Gene Transfer

An observational study in CLN6 and Batten Disease, sponsored by Emily de los Reyes. Active, not recruiting at 1 site in United States. Open to participants aged 12 Months and older. Per ClinicalTrials.gov, last updated 2025-10-02.

Sponsored by Emily de los Reyes · Observational

Study type
Observational
Model
Case-only
Time perspective
Prospective
Enrollment
10
Ages
12 Months and older
Sex
All
01

Study summary

This is a long-term safety and efficacy study in subjects with CLN6 Batten disease who previously received a single intrathecal administration of AT-GTX-501.

Read the detailed description

This is a long-term safety and efficacy study in subjects with CLN6 Batten disease (also know as variant late infantile neuronal ceroid lipofuscinosis associated with mutation(s) in the CLN6 gene [vLINCL6] disease),who previously received a single intrathecal administration of AT-GTX-501. The assessments described in this long-term follow-up (LTFU) study (AT-GTX-501-02) are performed following and in addition to the initial 2 years of post-treatment assessments in the treatment study (AT-GTX-501-01). In this LTFU study, subjects complete safety and efficacy assessments throughout the study's 3-year duration. Combining the duration of the initial treatment study and this LTFU study, the overall duration reflects a follow-up period up-to 5 years since gene transfer via AT-GTX-501.

The primary outcome for this study is to assess the long-term safety of AT-GTX-501 in subjects with CLN6 Batten disease.

The secondary outcome measure of this study is to assess the long-term efficacy of AT-GTX-501 in subjects with CLN6 Batten disease.

02

Conditions studied

  • CLN6
  • Batten Disease

Keywords

  • Neuronal ceroid lipofuscinosis
  • NCL
  • Gene Transfer
  • vLINCL6
03

Who can participate

Ages eligible
12 Months and older
Sexes eligible
All
Accepts healthy volunteers
No
Sampling method
Non-probability sample

Study population

The subject population in this Long-Term Follow Up study consists of subjects with CLN6 Batten disease who previously received AT-GTX-501 in the preceding study (AT-GTX-501-01).

Inclusion criteria

  • Subject received AT-GTX-501 (scAAV9.CB.CLN6) in the study "Phase I/IIa Gene Transfer Clinical Trial for Variant Late Infantile Neuronal Ceroid Lipofuscinosis, Delivering the CLN6 Gene by Self-Complementary AAV9."
  • Subject completed or prematurely discontinued from the study "Phase I/IIa Gene Transfer Clinical Trial for Variant Late Infantile Neuronal Ceroid Lipofuscinosis, Delivering the CLN6 Gene by Self-Complementary AAV9."
  • Subject has a legally authorized representative who has provided written informed consent and authorization for use and disclosure of personal health information or research-related health information.

Exclusion criteria

Exclusion Criteria:

  • None
04

Study design

Observational model
Case-only
Time perspective
Prospective
Enrollment
10 participants (actual)
Patient registry
No
Biospecimen retention
Samples with dna

Groups and cohorts

  • Subjects who received AT-GTX-501 gene transfer

    Subjects with CLN6 Batten disease who previously received AT-GTX-501 in the preceding study (Study AT-GTX-501-01).

    Genetic: AT-GTX-501

Interventions

  • GeneticAT-GTX-501

    No study drug is administered in this study. Subjects who received AT-GTX-501 in a previous trial will be evaluated in this trial for long-term safety and efficacy.

05

What researchers measure

Primary outcomes

  1. Long-term safety assessment based on Adverse Events (AEs)

    All AEs that occur during this study will be classified as treatment-emergent adverse events (TEAEs), as AT-GTX-501 was previously received by all subjects in this study.

    Time frame: up to 3 years

Secondary outcomes

  1. Hamburg Scale

    The Hamburg scale is an established tool to capture the rate of decline or regression. From the Hamburg Scale, the individual motor and language scores and the motor plus language aggregated score will be summarized.

    Time frame: up to 3 years

06

Study locations

1 site
  • Nationwide Children's Hosptial
    Columbus, Ohio 43205, United States
07

References and documents

Individual participant data

Plan to share: No

No publications or documents are linked to this record.

08

Registry details

Key details

Study ID
NCT04273243
Lead sponsor
Emily de los Reyes
Responsible party
Emily de los Reyes (Dr. Emily De Los Reyes, Nationwide Children's Hospital) — Sponsor-investigator
First posted
Feb 18, 2020
Start date
Jan 24, 2020
Primary completion
Dec 2026 (estimated)
Completion
Dec 2027 (estimated)
Last update
Oct 2, 2025

Study contacts

Emily de los Reyes, MD
principal investigator · Nationwide Children's Hospital

Oversight

Data monitoring committee
No
FDA-regulated drug
Yes
FDA-regulated device
No
View the source record on ClinicalTrials.gov ↗

Not currently enrolling

This study is active, not recruiting, as verified in Sep 2025. You cannot join it, but the record below documents what was studied.

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